Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl

We report the youngest case and extremely rare case of solitary jejunal Peutz-Jeghers polyp. The patient was 3-month-old girl who had been reduced by high-pressure enema for twice a week with episodes of intussusception at a referral hospital and underwent laparoscopic examination for a diagnosis of...

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Main Authors: Makoto Suzuki, Ryota Koyama, Yasuyuki Uchida, Kenjiro Ogushi, Sayaka Otake, Hideki Yamamoto, Ken Shirabe
Format: Article
Language:English
Published: Elsevier 2020-05-01
Series:Journal of Pediatric Surgery Case Reports
Online Access:http://www.sciencedirect.com/science/article/pii/S2213576620300671
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spelling doaj-3ede5c89c21a4333836b667df68dfc892020-11-25T03:18:19ZengElsevierJournal of Pediatric Surgery Case Reports2213-57662020-05-0156Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girlMakoto Suzuki0Ryota Koyama1Yasuyuki Uchida2Kenjiro Ogushi3Sayaka Otake4Hideki Yamamoto5Ken Shirabe6Division of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, Japan; Corresponding author. Division of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, Japan.Division of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDivision of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDivision of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDivision of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDivision of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDepartment of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanWe report the youngest case and extremely rare case of solitary jejunal Peutz-Jeghers polyp. The patient was 3-month-old girl who had been reduced by high-pressure enema for twice a week with episodes of intussusception at a referral hospital and underwent laparoscopic examination for a diagnosis of repeated intussusception. The intussusception was reduced laparoscopically. After reduction of the intussusception, an intraluminal bowel polyp was palpated. The polyp was excised and showed typical histological features of a Peutz-Jeghers (PJ) polyp. The patient presented with neither mucocutaneous pigmentation nor positive family history and was therefore characterized as a case of solitary PJ polyp without genetic investigation. The solitary jejunal PJ polyp is rare. Sone et al. [1] reported in 2000 for the first time. So far, only 5 cases of the solitary jejunal PJ polyp were reported and our case appears to be the sixth and the youngest case.Regular follow-up is essential in young children so that future manifestations of the PJS are not missed. A solitary PJ polyp, though very rare, should be kept in mind as a differential diagnosis in intestinal polyps causing small bowel intussusception. Keywords: Solitary Peutz-Jeghers polyp, Intussusception, Jejunumhttp://www.sciencedirect.com/science/article/pii/S2213576620300671
collection DOAJ
language English
format Article
sources DOAJ
author Makoto Suzuki
Ryota Koyama
Yasuyuki Uchida
Kenjiro Ogushi
Sayaka Otake
Hideki Yamamoto
Ken Shirabe
spellingShingle Makoto Suzuki
Ryota Koyama
Yasuyuki Uchida
Kenjiro Ogushi
Sayaka Otake
Hideki Yamamoto
Ken Shirabe
Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl
Journal of Pediatric Surgery Case Reports
author_facet Makoto Suzuki
Ryota Koyama
Yasuyuki Uchida
Kenjiro Ogushi
Sayaka Otake
Hideki Yamamoto
Ken Shirabe
author_sort Makoto Suzuki
title Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl
title_short Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl
title_full Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl
title_fullStr Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl
title_full_unstemmed Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl
title_sort solitary peutz–jeghers polyp of jejunum in 3-month-old girl
publisher Elsevier
series Journal of Pediatric Surgery Case Reports
issn 2213-5766
publishDate 2020-05-01
description We report the youngest case and extremely rare case of solitary jejunal Peutz-Jeghers polyp. The patient was 3-month-old girl who had been reduced by high-pressure enema for twice a week with episodes of intussusception at a referral hospital and underwent laparoscopic examination for a diagnosis of repeated intussusception. The intussusception was reduced laparoscopically. After reduction of the intussusception, an intraluminal bowel polyp was palpated. The polyp was excised and showed typical histological features of a Peutz-Jeghers (PJ) polyp. The patient presented with neither mucocutaneous pigmentation nor positive family history and was therefore characterized as a case of solitary PJ polyp without genetic investigation. The solitary jejunal PJ polyp is rare. Sone et al. [1] reported in 2000 for the first time. So far, only 5 cases of the solitary jejunal PJ polyp were reported and our case appears to be the sixth and the youngest case.Regular follow-up is essential in young children so that future manifestations of the PJS are not missed. A solitary PJ polyp, though very rare, should be kept in mind as a differential diagnosis in intestinal polyps causing small bowel intussusception. Keywords: Solitary Peutz-Jeghers polyp, Intussusception, Jejunum
url http://www.sciencedirect.com/science/article/pii/S2213576620300671
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