Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl
We report the youngest case and extremely rare case of solitary jejunal Peutz-Jeghers polyp. The patient was 3-month-old girl who had been reduced by high-pressure enema for twice a week with episodes of intussusception at a referral hospital and underwent laparoscopic examination for a diagnosis of...
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doaj-3ede5c89c21a4333836b667df68dfc892020-11-25T03:18:19ZengElsevierJournal of Pediatric Surgery Case Reports2213-57662020-05-0156Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girlMakoto Suzuki0Ryota Koyama1Yasuyuki Uchida2Kenjiro Ogushi3Sayaka Otake4Hideki Yamamoto5Ken Shirabe6Division of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, Japan; Corresponding author. Division of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, Japan.Division of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDivision of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDivision of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDivision of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDivision of Pediatric Surgery, Department of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanDepartment of General Surgical Science, Gunma University Graduate School of Medicine, 3-39-22 Showa, Maebashi, Gunma, 371-8511, JapanWe report the youngest case and extremely rare case of solitary jejunal Peutz-Jeghers polyp. The patient was 3-month-old girl who had been reduced by high-pressure enema for twice a week with episodes of intussusception at a referral hospital and underwent laparoscopic examination for a diagnosis of repeated intussusception. The intussusception was reduced laparoscopically. After reduction of the intussusception, an intraluminal bowel polyp was palpated. The polyp was excised and showed typical histological features of a Peutz-Jeghers (PJ) polyp. The patient presented with neither mucocutaneous pigmentation nor positive family history and was therefore characterized as a case of solitary PJ polyp without genetic investigation. The solitary jejunal PJ polyp is rare. Sone et al. [1] reported in 2000 for the first time. So far, only 5 cases of the solitary jejunal PJ polyp were reported and our case appears to be the sixth and the youngest case.Regular follow-up is essential in young children so that future manifestations of the PJS are not missed. A solitary PJ polyp, though very rare, should be kept in mind as a differential diagnosis in intestinal polyps causing small bowel intussusception. Keywords: Solitary Peutz-Jeghers polyp, Intussusception, Jejunumhttp://www.sciencedirect.com/science/article/pii/S2213576620300671 |
collection |
DOAJ |
language |
English |
format |
Article |
sources |
DOAJ |
author |
Makoto Suzuki Ryota Koyama Yasuyuki Uchida Kenjiro Ogushi Sayaka Otake Hideki Yamamoto Ken Shirabe |
spellingShingle |
Makoto Suzuki Ryota Koyama Yasuyuki Uchida Kenjiro Ogushi Sayaka Otake Hideki Yamamoto Ken Shirabe Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl Journal of Pediatric Surgery Case Reports |
author_facet |
Makoto Suzuki Ryota Koyama Yasuyuki Uchida Kenjiro Ogushi Sayaka Otake Hideki Yamamoto Ken Shirabe |
author_sort |
Makoto Suzuki |
title |
Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl |
title_short |
Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl |
title_full |
Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl |
title_fullStr |
Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl |
title_full_unstemmed |
Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl |
title_sort |
solitary peutz–jeghers polyp of jejunum in 3-month-old girl |
publisher |
Elsevier |
series |
Journal of Pediatric Surgery Case Reports |
issn |
2213-5766 |
publishDate |
2020-05-01 |
description |
We report the youngest case and extremely rare case of solitary jejunal Peutz-Jeghers polyp. The patient was 3-month-old girl who had been reduced by high-pressure enema for twice a week with episodes of intussusception at a referral hospital and underwent laparoscopic examination for a diagnosis of repeated intussusception. The intussusception was reduced laparoscopically. After reduction of the intussusception, an intraluminal bowel polyp was palpated. The polyp was excised and showed typical histological features of a Peutz-Jeghers (PJ) polyp. The patient presented with neither mucocutaneous pigmentation nor positive family history and was therefore characterized as a case of solitary PJ polyp without genetic investigation. The solitary jejunal PJ polyp is rare. Sone et al. [1] reported in 2000 for the first time. So far, only 5 cases of the solitary jejunal PJ polyp were reported and our case appears to be the sixth and the youngest case.Regular follow-up is essential in young children so that future manifestations of the PJS are not missed. A solitary PJ polyp, though very rare, should be kept in mind as a differential diagnosis in intestinal polyps causing small bowel intussusception. Keywords: Solitary Peutz-Jeghers polyp, Intussusception, Jejunum |
url |
http://www.sciencedirect.com/science/article/pii/S2213576620300671 |
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