Solitary Peutz–Jeghers polyp of jejunum in 3-month-old girl

We report the youngest case and extremely rare case of solitary jejunal Peutz-Jeghers polyp. The patient was 3-month-old girl who had been reduced by high-pressure enema for twice a week with episodes of intussusception at a referral hospital and underwent laparoscopic examination for a diagnosis of...

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Bibliographic Details
Main Authors: Makoto Suzuki, Ryota Koyama, Yasuyuki Uchida, Kenjiro Ogushi, Sayaka Otake, Hideki Yamamoto, Ken Shirabe
Format: Article
Language:English
Published: Elsevier 2020-05-01
Series:Journal of Pediatric Surgery Case Reports
Online Access:http://www.sciencedirect.com/science/article/pii/S2213576620300671
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Summary:We report the youngest case and extremely rare case of solitary jejunal Peutz-Jeghers polyp. The patient was 3-month-old girl who had been reduced by high-pressure enema for twice a week with episodes of intussusception at a referral hospital and underwent laparoscopic examination for a diagnosis of repeated intussusception. The intussusception was reduced laparoscopically. After reduction of the intussusception, an intraluminal bowel polyp was palpated. The polyp was excised and showed typical histological features of a Peutz-Jeghers (PJ) polyp. The patient presented with neither mucocutaneous pigmentation nor positive family history and was therefore characterized as a case of solitary PJ polyp without genetic investigation. The solitary jejunal PJ polyp is rare. Sone et al. [1] reported in 2000 for the first time. So far, only 5 cases of the solitary jejunal PJ polyp were reported and our case appears to be the sixth and the youngest case.Regular follow-up is essential in young children so that future manifestations of the PJS are not missed. A solitary PJ polyp, though very rare, should be kept in mind as a differential diagnosis in intestinal polyps causing small bowel intussusception. Keywords: Solitary Peutz-Jeghers polyp, Intussusception, Jejunum
ISSN:2213-5766